BibTex RIS Kaynak Göster

A rare cause of Ortner’s syndrome: giant pulmonary artery aneurysm secondary to Behçet’s disease

Yıl 2015, Cilt: 6 Sayı: 1, - , 10.05.2015
https://doi.org/10.5799/ahinjs.01.2015.01.0489

Öz

Behçet’ s disease is a systemic autoimmune vasculitis of unknown etiology. It causes serious disability by affecting both arteries and veins. Hoarseness due to compression of the left recurrent laringeus nerve resulting from pathologies of the heart and intrathoracic great vessels is defined as Ortner’s syndrome. The most common cause of Ortner’s syndrome is left atrial enlargement due to mitral stenosis. Various intrathoracic pathologies may also be the reason. Beside, Ortner’s syndrome due to primary pulmonary artery aneurysm as a feature of Behçet’s disease is relatively rare. Herein, we report a case of a 78 year old female patient presenting with hoarseness and diagnosed as Ortner’s syndrome resulting from a giant pulmonary artery aneurysm secondary to Behçet’ s disease. J Clin Exp Invest 2015; 6 (1): 69-71 Key words: Ortner’ s Syndrome, Pulmonary Artery Aneurysm, Behçet’s Disease

Kaynakça

  • Türkcü FM, Yüksel H, Uçmak D, et al. Demographic characteristics
  • and ocular involvement in Behçet patients in
  • Southeast Anatolia. J Clin Exp Invest 2013;4:339-342.
  • Küçük A, Albayrak İ, Bağçacı S, Küçükşen S, Tunç R.
  • Upper extremity thrombosis in Behçet. Dicle Med J
  • ;40:507-509.
  • Tüzün H, Hamuryudan V, Yıldırım S, et al. Surgical therapy
  • of pulmonary arterial aneurysms in Behçet’s syndrome.
  • Ann Thorac Surg 1996;61:733-735.
  • Day JR, Walesby RK. A spontaneous ductal aneurysm
  • presenting with left recurrent laryngeal nevre palsy. Ann
  • Thorac Surg 2001;72:608-609.
  • Kokotsakis J, Misthos P, Athanassiou T, et al. Acute Ortner’s
  • syndrome arising from ductus arteriosus aneurysm.
  • Tex Heart Inst J 2008;35:216-217.
  • Shih HH, Kang PL, Lin CY, et al. Main pulmonary artery
  • aneurysm. J Chin Med Assoc 2007;70:453-455.
  • Imazio M, Cecchi E, Giammaria M, et al. Main pulmonary
  • artery aneurysm: a case report and review of the literature.
  • Ital Heart J 2004;5:232-237.
  • Subramaniam V, Herle A, Mohammed N, et al. Ortner’s
  • syndrome: case series and literature review. Braz J Otorhinolaryngol
  • ;77:559-562.
  • Mulpuru SK, Vasavada BC, Punukollu GK, et al. Cardiovocal
  • syndrome: a systematic review. Heart Lung Circ
  • ;17:1-4.
  • Sakuma M, Demachi J, Suzuki J, et al. Proximal pulmonary
  • artery aneurysms in patients with pulmonary
  • artery hypertension: Complicated cases. Intern Med
  • ;46:1789-1793.
  • Bartter T, Irwin R, Nash G. Aneurysms of the pulmonary
  • arteries. Chest 1988;94:1065-1075.
  • Smalcelj A, Brida V, Samarzija M, et al. Giant, dissecting,
  • high-pressure pulmonary artery aneurysm:
  • case report of a 1-year natural course. Tex Heart Inst J
  • ;32:589-594.
  • Graham JK, Shehata B. Sudden death due to dissecting
  • pulmonary artery aneurysm: a case report and review of
  • the literature. Am J Forensic Med Pathol 2007;28:342-
  • -

Ortner sendromu’ nun nadir bir nedeni: Behçet hastalığına sekonder gelişen dev pulmoner arter anevrizması

Yıl 2015, Cilt: 6 Sayı: 1, - , 10.05.2015
https://doi.org/10.5799/ahinjs.01.2015.01.0489

Öz

Behçet Hastalığı nedeni bilinmeyen sistemik bir otoimmün vaskülittir. Hem arterleri hem de venleri tutarak ciddi sorunlara neden olabilir. Kalp ve intratorasik büyük damarların patolojilerine bağlı olarak sol rekürren laringeal sinirin kompresyonu sonucu gelişen ses kısıklığı Ortner Sendromu olarak ifade edilir. Ortner Sendromu’ nun en sık nedeni mitral darlığa bağlı olarak sol atriyum genişlemesidir. Çeşitli intratorasik patolojiler bu tablonun nedeni olabilir. Bununla birlikte Behçet Hastalığı sonucu gelişen pulmoner arter anevrizmasına bağlı Ortner Sendromu nispeten nadirdir. Biz burada ses kısıklığı ile başvuran ve yapılan incelemeler sonucunda Behçet Hastalığı’ na bağlı dev pulmoner arter anevrizması sonucu gelişen Ortner Sendromu olarak tanı alan 78 yaşında bir bayan hastayı sunuyoruz

Kaynakça

  • Türkcü FM, Yüksel H, Uçmak D, et al. Demographic characteristics
  • and ocular involvement in Behçet patients in
  • Southeast Anatolia. J Clin Exp Invest 2013;4:339-342.
  • Küçük A, Albayrak İ, Bağçacı S, Küçükşen S, Tunç R.
  • Upper extremity thrombosis in Behçet. Dicle Med J
  • ;40:507-509.
  • Tüzün H, Hamuryudan V, Yıldırım S, et al. Surgical therapy
  • of pulmonary arterial aneurysms in Behçet’s syndrome.
  • Ann Thorac Surg 1996;61:733-735.
  • Day JR, Walesby RK. A spontaneous ductal aneurysm
  • presenting with left recurrent laryngeal nevre palsy. Ann
  • Thorac Surg 2001;72:608-609.
  • Kokotsakis J, Misthos P, Athanassiou T, et al. Acute Ortner’s
  • syndrome arising from ductus arteriosus aneurysm.
  • Tex Heart Inst J 2008;35:216-217.
  • Shih HH, Kang PL, Lin CY, et al. Main pulmonary artery
  • aneurysm. J Chin Med Assoc 2007;70:453-455.
  • Imazio M, Cecchi E, Giammaria M, et al. Main pulmonary
  • artery aneurysm: a case report and review of the literature.
  • Ital Heart J 2004;5:232-237.
  • Subramaniam V, Herle A, Mohammed N, et al. Ortner’s
  • syndrome: case series and literature review. Braz J Otorhinolaryngol
  • ;77:559-562.
  • Mulpuru SK, Vasavada BC, Punukollu GK, et al. Cardiovocal
  • syndrome: a systematic review. Heart Lung Circ
  • ;17:1-4.
  • Sakuma M, Demachi J, Suzuki J, et al. Proximal pulmonary
  • artery aneurysms in patients with pulmonary
  • artery hypertension: Complicated cases. Intern Med
  • ;46:1789-1793.
  • Bartter T, Irwin R, Nash G. Aneurysms of the pulmonary
  • arteries. Chest 1988;94:1065-1075.
  • Smalcelj A, Brida V, Samarzija M, et al. Giant, dissecting,
  • high-pressure pulmonary artery aneurysm:
  • case report of a 1-year natural course. Tex Heart Inst J
  • ;32:589-594.
  • Graham JK, Shehata B. Sudden death due to dissecting
  • pulmonary artery aneurysm: a case report and review of
  • the literature. Am J Forensic Med Pathol 2007;28:342-
  • -
Toplam 40 adet kaynakça vardır.

Ayrıntılar

Birincil Dil İngilizce
Bölüm Olgu Sunumu
Yazarlar

Abdullah Çelik Bu kişi benim

Ahmet Karagöz

Erdal Seren Bu kişi benim

Sefer Usta Bu kişi benim

Aslı Vural Bu kişi benim

Zeki Günaydın Bu kişi benim

Osman Bektaş Bu kişi benim

Yayımlanma Tarihi 10 Mayıs 2015
Yayımlandığı Sayı Yıl 2015 Cilt: 6 Sayı: 1

Kaynak Göster

APA Çelik, A., Karagöz, A., Seren, E., Usta, S., vd. (2015). A rare cause of Ortner’s syndrome: giant pulmonary artery aneurysm secondary to Behçet’s disease. Journal of Clinical and Experimental Investigations, 6(1). https://doi.org/10.5799/ahinjs.01.2015.01.0489
AMA Çelik A, Karagöz A, Seren E, Usta S, Vural A, Günaydın Z, Bektaş O. A rare cause of Ortner’s syndrome: giant pulmonary artery aneurysm secondary to Behçet’s disease. J Clin Exp Invest. Mayıs 2015;6(1). doi:10.5799/ahinjs.01.2015.01.0489
Chicago Çelik, Abdullah, Ahmet Karagöz, Erdal Seren, Sefer Usta, Aslı Vural, Zeki Günaydın, ve Osman Bektaş. “A Rare Cause of Ortner’s Syndrome: Giant Pulmonary Artery Aneurysm Secondary to Behçet’s Disease”. Journal of Clinical and Experimental Investigations 6, sy. 1 (Mayıs 2015). https://doi.org/10.5799/ahinjs.01.2015.01.0489.
EndNote Çelik A, Karagöz A, Seren E, Usta S, Vural A, Günaydın Z, Bektaş O (01 Mayıs 2015) A rare cause of Ortner’s syndrome: giant pulmonary artery aneurysm secondary to Behçet’s disease. Journal of Clinical and Experimental Investigations 6 1
IEEE A. Çelik, “A rare cause of Ortner’s syndrome: giant pulmonary artery aneurysm secondary to Behçet’s disease”, J Clin Exp Invest, c. 6, sy. 1, 2015, doi: 10.5799/ahinjs.01.2015.01.0489.
ISNAD Çelik, Abdullah vd. “A Rare Cause of Ortner’s Syndrome: Giant Pulmonary Artery Aneurysm Secondary to Behçet’s Disease”. Journal of Clinical and Experimental Investigations 6/1 (Mayıs 2015). https://doi.org/10.5799/ahinjs.01.2015.01.0489.
JAMA Çelik A, Karagöz A, Seren E, Usta S, Vural A, Günaydın Z, Bektaş O. A rare cause of Ortner’s syndrome: giant pulmonary artery aneurysm secondary to Behçet’s disease. J Clin Exp Invest. 2015;6. doi:10.5799/ahinjs.01.2015.01.0489.
MLA Çelik, Abdullah vd. “A Rare Cause of Ortner’s Syndrome: Giant Pulmonary Artery Aneurysm Secondary to Behçet’s Disease”. Journal of Clinical and Experimental Investigations, c. 6, sy. 1, 2015, doi:10.5799/ahinjs.01.2015.01.0489.
Vancouver Çelik A, Karagöz A, Seren E, Usta S, Vural A, Günaydın Z, Bektaş O. A rare cause of Ortner’s syndrome: giant pulmonary artery aneurysm secondary to Behçet’s disease. J Clin Exp Invest. 2015;6(1).